Authors

  • Kakhkharova N.Kh.
    Republican Specialized Scientific and Practical Medical Center of Hematology, Uzbekistan
  • Kayumov A.A.
    Republican Specialized Scientific and Practical Medical Center of Hematology, Uzbekistan

DOI:

https://doi.org/10.71337/inlibrary.uz.ijasr.131448

Keywords:

Genetic mechanisms neuropathies immune system

Abstract

The article discusses the genetic mechanisms underlying the development of neuropathies in myeloma - a tumor of bone marrow plasma cells. Although these mechanisms are not yet fully understood, research points to several potential factors, including mutations in myeloma cell lineage-associated genes such as the MMSET/NSD2 gene and transcription factors such as IRF4. Another important factor is the immune system disorder that accompanies myeloma and can lead to damage to nerve fibers. More detailed studies are required to fully understand the genetic mechanisms of the development of neuropathies in myeloma.


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Volume 03 Issue 11-2023

184



International Journal of Advance Scientific Research
(ISSN

2750-1396)

VOLUME

03

ISSUE

11

Pages:

184-192

SJIF

I

MPACT

FACTOR

(2021:

5.478

)

(2022:

5.636

)

(2023:

6.741

)

OCLC

1368736135















































A

BSTRACT

The article discusses the genetic mechanisms underlying the development of neuropathies in myeloma -
a tumor of bone marrow plasma cells. Although these mechanisms are not yet fully understood, research
points to several potential factors, including mutations in myeloma cell lineage-associated genes such as
the MMSET/NSD2 gene and transcription factors such as IRF4. Another important factor is the immune
system disorder that accompanies myeloma and can lead to damage to nerve fibers. More detailed
studies are required to fully understand the genetic mechanisms of the development of neuropathies in
myeloma.

K

EYWORDS

Genetic mechanisms, neuropathies, myeloma, mutations, MMSET/NSD2, IRF4, immune system, nerve
fibers.

I

NTRODUCTION

Myeloma is a tumor of bone marrow plasma cells
that can lead to various complications, including
neuropathies. Although the genetic mechanisms
underlying the development of neuropathies in

myeloma are still being studied, some studies
point to several potential factors.

One such factor is the presence of mutations in
genes associated with the myeloma cell line. For

Journal

Website:

http://sciencebring.co
m/index.php/ijasr

Copyright:

Original

content from this work
may be used under the
terms of the creative
commons

attributes

4.0 licence.

Research Article

GENETIC MECHANISMS OF DEVELOPMENT OF
NEUROPATHIES IN MYELOMA


Submission Date:

November 09, 2023,

Accepted Date:

November 14, 2023,

Published Date:

November 19, 2023

Crossref doi:

https://doi.org/10.37547/ijasr-03-11-31


Kakhkharova N.Kh.

Republican Specialized Scientific and Practical Medical Center of Hematology, Uzbekistan

Kayumov A.A.

Republican Specialized Scientific and Practical Medical Center of Hematology, Uzbekistan


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Volume 03 Issue 11-2023

185



International Journal of Advance Scientific Research
(ISSN

2750-1396)

VOLUME

03

ISSUE

11

Pages:

184-192

SJIF

I

MPACT

FACTOR

(2021:

5.478

)

(2022:

5.636

)

(2023:

6.741

)

OCLC

1368736135















































example, mutations in the MMSET/NSD2 gene
and genes encoding transcription factors such as
IRF4 are thought to be associated with
neuropathies in myeloma.

In addition, immune system disorders may also
play a role in the development of neuropathies in
myeloma. Myeloma causes immune system
dysfunction and inflammation, which can
damage nerve fibers.

More detailed studies and analyzes of the genetic
mechanisms of the development of neuropathies
in myeloma are necessary to fully understand
this process. But existing evidence points to the
importance of genetic factors and immune
system dysfunction in this context.

Gene polymorphism, polymorphism is a
structural difference between alternative
variants of a gene (usually normal and mutant).
The occurrence of gene variants is caused by
mutations. Genotyping of polymorphic loci of
selected immune response genes revealed
differences in the frequency of detection of
haplotypes of the TLR6(Ser249Pro), IL1β (G-
1473C), IL2(T-330G), IL4(C-589T) and IL10(G-
1082A) genes.

Interleukin-4 (IL-4) is a cytokine that plays a
significant role in immune responses and is
involved in the growth and survival of certain
immune cells, including B cells and plasma cells.
Changes in IL-4 levels due to genetic
polymorphisms can potentially influence the
immune response and consequently the risk or
progression of diseases such as myeloma.

The C-589T polymorphism, also known as
rs2243250, is a genetic variation located in the
promoter region of the IL4 (interleukin-4) gene.
This polymorphism has been investigated in
various diseases, including myeloma, due to its
potential role in modulating interleukin-4
production.

In myeloma, it has been found that IL-4 levels
may be elevated in both the blood and myeloma
cells of patients. This cytokine may stimulate the
growth and survival of myeloma cells and may
also help protect them from the cellular immune
response. Moreover, IL-4 may participate in the
formation of the tumor microenvironment,
creating favorable conditions for the progression
of myeloma.

Studies confirm that IL-4 plays an important role
in the pathogenesis and progression of myeloma,
and may be a potential target for new
therapeutic approaches. Further studies are
needed to more fully understand the role of IL-4
and its impact on the development and
progression of myeloma.

To study allele frequency and genotype
frequency distribution in myeloma, a study was
conducted in which participants were divided
into two groups: main and control. The total
number of participants in the main group was
n=94, of which grade I neuropathy: n = 22, grade
II neuropathy: n = 44, grade III neuropathy: n =
28. The study results are shown in Table 1:


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(2022:

5.636

)

(2023:

6.741

)

OCLC

1368736135















































Num

Group

Allele frequency

Genotype distribution frequency

C

T

C/C

C/T

T/T

n

%

n %

n %

n %

n %

1

Main group (n
= 94)

117 62,2 71 37,8 42 44,7 33 35,1 19 20,2

2

grade

I

neuropathy (n
= 22)

25

56,8 19 43,2 8

36,4 9

40,9 5

22,7

3

grade

II

neuropathy (n
= 44)

63

71,6 25 28,4 26 59,1 11 25

7

15,9

4

grade

III

neuropathy (n
= 28)

29

51,8 27 48,2 8

28,6 13 46,4 7

25

5

Control group
(n = 90)

130 72,2 50 27,8 51 56,7 28 31,1 11 12,2

Table 1. Percentage of mutation frequencies in the main and experimental groups

The study also examined the prognostic effectiveness of the studied genetic markers (C-589T
polymorphism in the IL4 gene). The results are shown in Table 2.

Factor

Groups

SE

SP

AUC

OR

95%CI

p

C

Main group// Control

group

0,62

0,28

0,45

0,63

0,4 - 0,98

0,59

grade I neuropathy //

Control group

0,57

0,28

0,43

0,51

0,26 - 0,99

0,28

grade II neuropathy //

Control group

0,72

0,28

0,5

0,97

0,56 - 1,68

0,33

grade III neuropathy

// Control group

0,52

0,28

0,4

0,41

0,22 - 0,76

0,35

grade I neuropathy //

grade II neuropathy

0,57

0,28

0,43

0,52

0,24 - 1,11

0,43

grade I neuropathy //

grade III neuropathy

0,06

0,48

0,27

0,05

0,01 - 0,25

0,41

grade II neuropathy //

grade III neuropathy

0,72

0,48

0,6

2,35

1,17 - 4,71

0,48


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Volume 03 Issue 11-2023

187



International Journal of Advance Scientific Research
(ISSN

2750-1396)

VOLUME

03

ISSUE

11

Pages:

184-192

SJIF

I

MPACT

FACTOR

(2021:

5.478

)

(2022:

5.636

)

(2023:

6.741

)

OCLC

1368736135















































Factor

Groups

SE

SP

AUC

OR

95%CI

p

T

Main group // Control

group

0,72

0,38

0,55

1,58

1,02 - 2,45

0,41

grade I neuropathy //

Control group

0,72

0,43

0,58

1,98

1,01 - 3,89

0,72

grade II neuropathy //

Control group

0,72

0,28

0,5

1,03

0,6 - 1,76

0,67

grade III neuropathy

// Control group

0,72

0,48

0,6

2,42

1,32 - 4,45

0,65

grade I neuropathy //

grade II neuropathy

0,72

0,43

0,58

1,92

0,9 - 4,08

0,57

grade I neuropathy //

grade III neuropathy

0,52

0,43

0,48

0,82

0,38 - 1,78

0,59

grade II neuropathy //

grade III neuropathy

0,52

0,28

0,4

0,43

0,22 - 0,85

0,52

Factor

Groups

SE

SP

AUC

OR

95%CI

p

C/C

Main group // Control

group

0,45

0,43

0,44

0,62

0,35 - 1,1

0,57

grade I neuropathy //

Control group

0,36

0,43

0,4

0,44

0,17 - 1,13

0,26

grade II neuropathy //

Control group

0,59

0,43

0,51

1,1

0,55 - 2,22

0,32

grade III neuropathy //

Control group

0,29

0,43

0,36

0,31

0,13 - 0,75

0,34

grade I neuropathy //

grade II neuropathy

0,36

0,41

0,39

0,4

0,14 - 1,12

0,44

grade I neuropathy //

grade III neuropathy

0,07

0,71

0,39

0,2

0,03 - 1,4

0,41

grade II neuropathy //

grade III neuropathy

0,59

0,71

0,65

3,61

1,33 - 9,76

0,47

Factor

Groups

SE

SP

AUC

OR

95%CI

p

C/T

Main group // Control

group

0,35

0,69

0,52

1,2

0,64 - 2,23

0,5


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(ISSN

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VOLUME

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ISSUE

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Pages:

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(2021:

5.478

)

(2022:

5.636

)

(2023:

6.741

)

OCLC

1368736135















































grade I neuropathy //

Control group

0,41

0,69

0,55

1,53

0,59 - 3,96

0,17

grade II neuropathy //

Control group

0,25

0,69

0,47

0,74

0,33 - 1,66

0,35

grade III neuropathy

// Control group

0,46

0,69

0,58

1,92

0,81 - 4,54

0,19

grade I neuropathy //

grade II neuropathy

0,41

0,75

0,58

2,08

0,7 - 6,14

0,28

grade I neuropathy //

grade III neuropathy

0,41

0,54

0,48

0,8

0,26 - 2,45

0,46

grade II neuropathy //

grade III neuropathy

0,25

0,54

0,4

0,38

0,14 - 1,04

0,69

Factor

Groups

SE

SP

AUC

OR

95%CI

p

T/T

Main group // Control

group

0,2

0,88

0,54

1,82

0,82 - 4,05

0,49

grade I neuropathy //

Control group

0,23

0,88

0,56

2,11

0,66 - 6,73

0,18

grade II neuropathy //

Control group

0,16

0,88

0,52

1,36

0,49 - 3,79

0,32

grade III neuropathy

// Control group

0,25

0,88

0,57

2,39

0,84 - 6,76

0,21

grade I neuropathy //

grade II neuropathy

0,23

0,84

0,54

1,55

0,44 - 5,51

0,31

grade I neuropathy //

grade III neuropathy

0,23

0,75

0,49

0,88

0,23 - 3,37

0,45

grade II neuropathy //

grade III neuropathy

0,16

0,75

0,46

0,57

0,18 - 1,82

0,64

Studies indicate that the frequency of allelic and
genotypic variants of the C-589T polymorphism
in the IL4 gene may vary among different groups
of myeloma patients.

For example, patients with multiple myeloma
(MM) were found to have a significantly higher
frequency of the T allele of the C-589T
polymorphism compared to controls. We also

note that the presence of a homozygous TT
genotype was associated with an earlier age of
onset and progression of MM.

In general, we can see the differences in the
frequency of alleles and genotypes of the C-589T
polymorphism in the IL4 gene between groups of
myeloma patients in Table 3.


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International Journal of Advance Scientific Research
(ISSN

2750-1396)

VOLUME

03

ISSUE

11

Pages:

184-192

SJIF

I

MPACT

FACTOR

(2021:

5.478

)

(2022:

5.636

)

(2023:

6.741

)

OCLC

1368736135















































Alleles

and

genotypes

Number of alleles and

genotypes examined

χ2

p

RR

95%CI

OR

95%CI

Main group

Control group

n

%

n

%

C

117

62,2

130

72,2

4,2

0,05

0,9

0,58 - 1,27

0,6

0,41 - 0,98

T

71

37,8

50

27,8

4,2

0,05

1,2

0,72 - 1,87

1,6

1,02 - 2,45

C/C

42

44,7

51

56,7

2,6

0,20

0,8

0,45 - 1,38

0,6

0,35 - 1,1

C/T

33

35,1

28

31,1

0,3

0,60

1,1

0,64 - 2

1,2

0,65 - 2,22

T/T

19

20,2

11

12,2

2,2

0,20

1,7

0,89 - 3,08

1,8

0,82 - 4,05

Alleles

and

genotypes

Number of alleles and

genotypes examined

χ2

p

RR

95%CI

OR

95%CI

grade I

neuropathy

grade II

neuropathy

n

%

n

%

C

25

56,8

63

71,6

2,9

0,10

0,8

0,31 - 2,01

0,5

0,25 - 1,11

T

19

43,2

25

28,4

2,9

0,10

1,3

0,71 - 2,22

1,9

0,9 - 4,06

C/C

8

36,4

26

59,1

3,0

0,10

0,6

0,15 - 2,53

0,4

0,14 - 1,12

C/T

9

40,9

11

25,0

1,8

0,20

1,6

0,44 - 6,06

2,1

0,7 - 6,12

T/T

5

22,7

7

15,9

0,5

0,50

1,4

0,31 - 6,54

1,6

0,43 - 5,58

Alleles

and

genotypes

Number of alleles and

genotypes examined

χ2

p

RR

95%CI

OR

95%CI

grade I

neuropathy

grade III

neuropathy

n

%

n

%

C

25

56,8

29

51,8

0,3

0,70

1,1

0,46 - 2,64

1,2

0,55 - 2,71

T

19

43,2

27

48,2

0,3

0,70

0,9

0,46 - 1,8

0,8

0,37 - 1,81

C/C

8

36,4

8

28,6

0,3

0,60

1,3

0,37 - 4,41

1,4

0,43 - 4,71

C/T

9

40,9

13

46,4

0,2

0,70

0,9

0,25 - 3,09

0,8

0,26 - 2,47

T/T

5

22,7

7

25,0

0,0

0,90

0,9

0,21 - 4,01

0,9

0,24 - 3,28

Alleles

and

genotypes

Number of alleles and

genotypes examined

χ2

p

RR

95%CI

OR

95%CI

grade I

neuropathy

Control group

n

%

n

%

C

25

56,8

130

72,2

3,9

0,05

0,8

0,28 - 2,2

0,5

0,26 - 0,99


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Volume 03 Issue 11-2023

190



International Journal of Advance Scientific Research
(ISSN

2750-1396)

VOLUME

03

ISSUE

11

Pages:

184-192

SJIF

I

MPACT

FACTOR

(2021:

5.478

)

(2022:

5.636

)

(2023:

6.741

)

OCLC

1368736135















































T

19

43,2

50

27,8

3,9

0,05

1,3

0,93 - 1,74

2,0

1,01 - 3,87

C/C

8

36,4

51

56,7

2,9

0,10

0,6

0,14 - 2,99

0,4

0,17 - 1,13

C/T

9

40,9

28

31,1

0,8

0,40

1,3

0,3 - 5,75

1,5

0,59 - 3,99

T/T

5

22,7

11

12,2

1,6

0,30

1,9

0,35 - 9,74

2,1

0,66 - 6,75

Alleles

and

genotypes

Number of alleles and

genotypes examined

χ2

p

RR

95%CI

OR

95%CI

grade II

neuropathy

grade III

neuropathy

n

%

n

%

C

63

71,6

29

51,8

5,8

0,03

1,4

0,75 - 2,56

2,3

1,17 - 4,69

T

25

28,4

27

48,2

5,8

0,03

0,7

0,33 - 1,58

0,4

0,21 - 0,85

C/C

26

59,1

8

28,6

6,4

0,03

2,1

0,98 - 4,39

3,6

1,33 - 9,77

C/T

11

25,0

13

46,4

3,5

0,10

0,5

0,21 - 1,37

0,4

0,14 - 1,04

T/T

7

15,9

7

25,0

0,9

0,40

0,6

0,21 - 1,9

0,6

0,18 - 1,83

Alleles

and

genotypes

Number of alleles and

genotypes examined

χ2

p

RR

95%CI

OR

95%CI

grade II

neuropathy

Control group

n

%

n

%

C

63

71,6

130

72,2

0,0

0,95

1,0

0,47 - 2,08

1,0

0,55 - 1,71

T

25

28,4

50

27,8

0,0

0,95

1,0

0,7 - 1,46

1,0

0,59 - 1,82

C/C

26

59,1

51

56,7

0,1

0,80

1,0

0,4 - 2,74

1,1

0,53 - 2,3

C/T

11

25,0

28

31,1

0,5

0,50

0,8

0,26 - 2,46

0,7

0,33 - 1,67

T/T

7

15,9

11

12,2

0,3

0,60

1,3

0,37 - 4,54

1,4

0,49 - 3,78

Alleles

and

genotypes

Number of alleles and

genotypes examined

χ2

p

RR

95%CI

OR

95%CI

grade III

neuropathy

Control group

n

%

n

%

C

29

51,8

130

72,2

8,1

0,01

0,7

0,3 - 1,73

0,4

0,22 - 0,76

T

27

48,2

50

27,8

8,1

0,01

1,4

0,98 - 1,98

2,4

1,32 - 4,45

C/C

8

28,6

51

56,7

6,7

0,01

0,5

0,12 - 2,13

0,3

0,13 - 0,75

C/T

13

46,4

28

31,1

2,2

0,20

1,5

0,43 - 5,22

1,9

0,81 - 4,53

T/T

7

25,0

11

12,2

2,7

0,20

2,0

0,53 - 7,95

2,4

0,84 - 6,79


background image

Volume 03 Issue 11-2023

191



International Journal of Advance Scientific Research
(ISSN

2750-1396)

VOLUME

03

ISSUE

11

Pages:

184-192

SJIF

I

MPACT

FACTOR

(2021:

5.478

)

(2022:

5.636

)

(2023:

6.741

)

OCLC

1368736135















































Alleles

and

genotypes

Number of alleles and

genotypes examined

χ2

p

RR

95%CI

OR

95%CI

grade I

neuropathy

grade II

neuropathy

n

%

n

%

C

25

56,8

63

71,6

2,9

0,10

0,8

0,31 - 2,01

0,5

0,25 - 1,11

T

19

43,2

25

28,4

2,9

0,10

1,3

0,71 - 2,22

1,9

0,9 - 4,06

C/C

8

36,4

26

59,1

3,0

0,10

0,6

0,15 - 2,53

0,4

0,14 - 1,12

C/T

9

40,9

11

25,0

1,8

0,20

1,6

0,44 - 6,06

2,1

0,7 - 6,12

T/T

5

22,7

7

15,9

0,5

0,50

1,4

0,31 - 6,54

1,6

0,43 - 5,58

Alleles

and

genotypes

Number of alleles and

genotypes examined

χ2

p

RR

95%CI

OR

95%CI

grade I

neuropathy

grade III

neuropathy

n

%

n

%

C

25

56,8

29

51,8

0,3

0,70

1,1

0,46 - 2,64

1,2

0,55 - 2,71

T

19

43,2

27

48,2

0,3

0,70

0,9

0,46 - 1,8

0,8

0,37 - 1,81

C/C

8

36,4

8

28,6

0,3

0,60

1,3

0,37 - 4,41

1,4

0,43 - 4,71

C/T

9

40,9

13

46,4

0,2

0,70

0,9

0,25 - 3,09

0,8

0,26 - 2,47

T/T

5

22,7

7

25,0

0,0

0,90

0,9

0,21 - 4,01

0,9

0,24 - 3,28

Alleles

and

genotypes

Number of alleles and

genotypes examined

χ2

p

RR

95%CI

OR

95%CI

grade II

neuropathy

grade III

neuropathy

n

%

n

%

C

63

71,6

29

51,8

5,8

0,03

1,4

0,75 - 2,56

2,3

1,17 - 4,69

T

25

28,4

27

48,2

5,8

0,03

0,7

0,33 - 1,58

0,4

0,21 - 0,85

C/C

26

59,1

8

28,6

6,4

0,03

2,1

0,98 - 4,39

3,6

1,33 - 9,77

C/T

11

25,0

13

46,4

3,5

0,10

0,5

0,21 - 1,37

0,4

0,14 - 1,04

T/T

7

15,9

7

25,0

0,9

0,40

0,6

0,21 - 1,9

0,6

0,18 - 1,83

In conclusion of the article on the genetic
mechanisms of the development of neuropathies
in myeloma, the following can be noted:

1. The development of neuropathies in myeloma
may be associated with genetic factors. Research
suggests that certain genetic variants may


background image

Volume 03 Issue 11-2023

192



International Journal of Advance Scientific Research
(ISSN

2750-1396)

VOLUME

03

ISSUE

11

Pages:

184-192

SJIF

I

MPACT

FACTOR

(2021:

5.478

)

(2022:

5.636

)

(2023:

6.741

)

OCLC

1368736135















































increase the risk of developing neuropathies in
myeloma patients.

2. Some genetic polymorphisms, such as
polymorphisms in genes associated with drug
metabolism or inflammation, may influence an
individual's

susceptibility

to

developing

neuropathies.

3. Genetic variants may influence various
pathways and mechanisms associated with
neuropathy in myeloma, such as nerve fiber
damage, vasculitis, and inflammation.

4. Further research is needed to better
understand the genetic mechanisms of the
development of neuropathies in myeloma and to
develop personalized approaches to their
prevention and treatment.

Overall, genetic factors are important in the
development of neuropathies in myeloma, and
understanding these mechanisms may help
improve the diagnosis, prognosis, and treatment
of this complication.

R

EFERENCES

1.

Palumbo, A., & Anderson, K. (2011). Multiple
myeloma. New England Journal of Medicine,
364(11), 1046-1060.

2.

Rajkumar, S. V., & Kumar, S. (2016). Multiple
myeloma: diagnosis and treatment. Mayo
Clinic Proceedings, 91(1), 101-119.

3.

Dimopoulos, M. A., Terpos, E., & Niesvizky, R.
(2019). How to treat patients with
relapsed/refractory

multiple

myeloma.

Leukemia, 33(4), 1099-1112.

4.

Cavo, M., Terpos, E., & Nanni, C. (2020). Role
of imaging techniques in the management of
multiple myeloma: a consensus statement
from the International Myeloma Working
Group. The Lancet Oncology, 21(8), e360-
e376.

5.

Usmani, S. Z., Heuck, C., & Mitchell, A. (2019).
Extramedullary disease portends poor
prognosis in multiple myeloma and is over-
represented in high-risk disease even in the
era of novel agents. Haematologica, 104(5),
e211-e214.

6.

Sonneveld, P., Avet-Loiseau, H., & Lonial, S.
(2016). Treatment of multiple myeloma with
high-risk cytogenetics: a consensus of the
International Myeloma Working Group.
Blood, 127(24), 2955-2962.

References

Palumbo, A., & Anderson, K. (2011). Multiple myeloma. New England Journal of Medicine, 364(11), 1046-1060.

Rajkumar, S. V., & Kumar, S. (2016). Multiple myeloma: diagnosis and treatment. Mayo Clinic Proceedings, 91(1), 101-119.

Dimopoulos, M. A., Terpos, E., & Niesvizky, R. (2019). How to treat patients with relapsed/refractory multiple myeloma. Leukemia, 33(4), 1099-1112.

Cavo, M., Terpos, E., & Nanni, C. (2020). Role of imaging techniques in the management of multiple myeloma: a consensus statement from the International Myeloma Working Group. The Lancet Oncology, 21(8), e360-e376.

Usmani, S. Z., Heuck, C., & Mitchell, A. (2019). Extramedullary disease portends poor prognosis in multiple myeloma and is over-represented in high-risk disease even in the era of novel agents. Haematologica, 104(5), e211-e214.

Sonneveld, P., Avet-Loiseau, H., & Lonial, S. (2016). Treatment of multiple myeloma with high-risk cytogenetics: a consensus of the International Myeloma Working Group. Blood, 127(24), 2955-2962.